Objective: To describe the management of congenital lacrimal fistulas and to present two cases of congenital lacrimal fistulas with surgical resolution. A brief review of the literature.
Patients and Methods: Two pediatric patients with congenital lacrimal fistulas were evaluated and treated surgically.
Results: The surgical technique used in each case and its outcome are presented.
Conclusion: Congenital lacrimal fistulas are developmental anomalies of the lacrimal system that can be symptomatic, causing epiphora or infections such as fistulas, dacryocystitis, or conjunctivitis. Resection of the fistulous tract alone or in conjunction with tear duct intubation or dacryocystorhinostomy are the surgical treatment options.
Chaung JQ, Sundar G, Ali MJ. Congenital lacrimal fistula: A major review. Orbit 2016 Aug; 35(4):212-220.
Sullivan TJ, Clarke MP, Morin JD, Pashby RC. The surgical management of congenital lacrimal fistulae. Austral New Zealand J Ophthalmolol 1992; 20:109-114.
Kim GN, Huh HD, Park JM, Seo SW. An atypical case of lacrimal sac fistula located on the temporal side of the lateral canthus. Korean J Ophthalmol 2012 Dec; 26(6):462-464.
Maden A, Yilmaz S, Ture M. Hereditary lacrimal fistula. Orbit 2008; 27:69-72.
Al-Salem K, Gibson A, Dolman PJ. Management of congenital lacrimal (anlage) fistula. Br J Ophthalmol 2014; 98:1435-1436.
Keseru M, Richard G, Galambos P. A case of bilateral lacrimal fistula associates with Down Syndrome. Orbit 2010; 29:153-154.
Harrison AR, Dailey RA, Wobig JL. Bilateral congenital lacrimal anlage ducts (lacrimal fistula) in a patient with the VACTERL association. Ophthal Plast Reconstrut Surg 2002; 18:149-150.
Elmann S, Hanson SA, Bunce CN, Shinder R. Ectrodactyly ectodermal dysplasia clefting (eec) syndrome. A rare cause of congenital lacrimal anomalies. Ophthal Plast Reconstrut Surg 2015; 31:35-37.
Tien AM, Tien DR. Bilateral congenital lacrimal sac fistula in a patient with ectrodactyly ectodermal dysplasia-clefting syndrome. J Asso Pediatric Ophthalmol Strabismus 2006; 10:577-578.
Turan-Vural E, Atmaca F, Unlu C, Erdogan G, Bayramlat H. Unilateral lacrimal fistula in a patient with uterus didelphys and renal agenesis. Inter Ophthalmol 2012 Feb; 32(1):67-69.
Birchansky LD, Nerad JA, Kersten RC, Kulwin DR. Management of congenital lacrimal sac fistula. Arch Ophthalmol 1990; 108(3):388-390.
Choi YM, Jang Y, Kim N, Chung HK, Khwarg SI. The effect of lacrimal drainage abnormality on the surgical outcomes of congenital lacrimal fistula and vice versa. Eur J Ophthalmol 2002 Jan;32(1):108-114.
Omaran Z, Yimazbas P, Ornek K, Bilateral punctum atresia and lacrimal sac fistula in a child with CHARGE syndrome. Clinton Exp Ophthalmol 2009 Dec;37(9):894-895.
Ding J, Sun H, Li D. Persistent pediatric primary canaliculitis associated with congenital lacrimal fistula. Can J Ophthalmol. 2017 Oct;52(5):e161-163.
Levine J. Congenital fistula of the lacrimal sac. Am J Ophthalmol 1929;12:745-746.
Weidler WB. Congenital fistula of the lacrimal sac. Arch Ophthalmol 1915;44:295-296.
Kono S, Lee PAL, Kakizaki H, Takahashi Y. Dacryoendoscopic examination for location of internal orificio of congenital lacrimal fistula: A case series. Int J Pediatr Otorhinolaryngology 2010 Dec;139:110408.
Bothra N, Ali MJ. Radiofrequency-Assisted Endofistulectomy: Treating Coexisting Lacrimal Fistualae During Endoscopic Dacryocystorhinostomy. Ophthalmic Plasticity Reconstr Surgery. 2020 Nov/Dec;36(6):610-612.
Ali MJ, Bothra N. Radiofrequency-assisted endofistulectomy for a recurrent congenital lacrimal fistula. Orbit 2022 Dec;41(6):818-819.